Introduction: The UNITY study evaluates the efficacy and safety of nipocalimab, a neonatal Fc receptor blocker, in reducing the risk of fetal anemia, intrauterine transfusions (IUT), and poor outcomes for pregnancies at high risk of early-onset severe hemolytic disease of the fetus and newborn (EOS-HDFN).
Methods: This open-label, single-arm study (NCT03842189) enrolled RhD or Kell alloimmunized pregnant individuals with singleton pregnancies at high risk for EOS-HDFN based on a prior obstetric history of fetal loss, fetal hydrops, severe fetal anemia, or need for IUT at ≤24 weeks gestational age (GA) due to HDFN. Weekly 30 or 45 mg/kg intravenous nipocalimab was administered between 14-35 weeks GA, with delivery targeted for 37 weeks GA. Follow-up was 24 weeks postpartum for mothers and 96 weeks postnatal for infants. The primary efficacy endpoint is the proportion of participants with a live birth at ≥32 weeks GA without an IUT. Secondary endpoints for antenatal and postnatal management are reported.
Results: Of the total pregnancies (14), one pregnancy was not included due to early elective abortion for an unrelated reason. 54% (7/13) of participants achieved the primary efficacy endpoint of a live birth at >32 weeks GA without IUTs, with a median GA at delivery of 37 1/7 weeks (35 6/7–37 3/7). Twelve of 13 (92.3%) pregnancies resulted in a live birth with a median GA at delivery of 36 5/7 weeks (29 2/7–37 3/7). None of the 13 pregnancies developed fetal hydrops. One pregnancy resulted in fetal demise following complications of an IUT at 22 5/7 weeks GA. Of 12 live births, 11 (92%) neonates received phototherapy for median 87.0 hours (12–301). 50% (6/12) of neonates/infants received ≥1 simple transfusion in the first 12 weeks of life. The median number of simple transfusions was 2 (1–6), with 5 of 6 in pregnancies that received IUTs including 1 exchange transfusion. In 7 cases without an IUT, 1 infant had 1 simple transfusion. Four serious adverse events (SAEs) possibly related to nipocalimab occurred: fetal growth restriction, subchorionic hematoma, and fetal heart rate deceleration abnormality in one participant and placental abruption at delivery in another. One neonate delivered at 29 weeks developed a related SAE of neonatal respiratory distress. No maternal or neonatal/infant deaths occurred.
Conclusion: This study demonstrates the potential for nipocalimab to impact antenatal and postnatal management of fetal anemia in pregnancies at high risk for EOS-HDFN.